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It is considered a medical emergency and its standard treatment is based on plasma exchange associated with high doses of corticosteroids. Those patients refractory to standard treatment have a high risk of morbidity-mortality. Through this clinical case, a patient refractory to all the treatments is presented. She was treated whit caplacizumab that is humanized bivalent antibody acting against the domain A1 of the von Willebrand factor and prevents interaction with the glycoprotein Ib-IX-V (GPIb-IX-X). After one year from the end of treatment, the patient remains stable and asymptomatic. Caplacizumab is a good choice in those patients who do not respond to any of the standard treatments and that can lead to a decrease in mortality in patients with refractory thrombotic thrombocytopenic purpura. © 2020 Rizo LM, et al. This is an open-access article distributed under the terms of the Creative Commons Attribution License, which permits unrestricted use, distribution, and reproduction in any medium, provided the original author and source are credited. Lara Martín Rizo1* Noemí Gómez García1 Laura Llorente González2 Alfons Serrano Maestro2 Miriam Sánchez Mateo1 JaimePérez de Oteyza2 and José Manuel Ortega Gómez1 Caplacizumab Refractory Thrombotic thrombocytopenic purpura Antibody Platelets 2020-06-05T19:55:45+05:30 2020-06-05T19:55:46+05:30 2020-06-05T19:55:46+05:30 4 Adobe InDesign CS6 (Windows) uuid:52865d59-9107-4c77-81c4-8d556331335c xmp.did:FE00469DB0C7E411AEB789ACBE3823B3 xmp.id:27AC2B5638A7EA11A30DE45D3E5A9AE7 proof:pdf xmp.iid:26AC2B5638A7EA11A30DE45D3E5A9AE7 xmp.did:25700E8721B3E7119FB78DFA0FAB8027 xmp.did:FE00469DB0C7E411AEB789ACBE3823B3 default converted from application/x-indesign to application/pdf Adobe InDesign CS6 (Windows) / 2020-06-05T19:55:45+05:30 Rizo LM, García NG, González LL, Maestro AS, Mateo MS, et al. (2020) Caplacizumab: First Case of Thrombotic Thrombocytopenic PurpuraRefractory Treated in Spain outside Clinical Trial. J Drug Res Dev 6(2): dx.doi.org/10.16966/2470-1009.153 Lara Martín Rizo, Pharmacy Department, Hospital University HM Sanchinarro, Street Oña 10 Madrid, Spain, E-mail: lara.martinrizo@gmail.com http://dx.doi.org/10.16966/2470-1009.153 Adobe PDF Library 10.0.1 False endstream endobj 171 0 obj <> endobj xref 0 825 0000000000 65535 f 0000233279 00000 n 0000233715 00000 n 0000241598 00000 n 0000241657 00000 n 0000242204 00000 n 0000247351 00000 n 0000247463 00000 n 0000247576 00000 n 0000283834 00000 n 0000283869 00000 n 0000283945 00000 n 0000284257 00000 n 0000288287 00000 n 0000369692 00000 n 0000369752 00000 n 0000370243 00000 n 0000370602 00000 n 0000376984 00000 n 0000377044 00000 n 0000377594 00000 n 0000377985 00000 n 0000378391 00000 n 0000380335 00000 n 0000395805 00000 n 0000395882 00000 n 0000396081 00000 n 0000396118 00000 n 0000400373 00000 n 0000400743 00000 n 0000400869 00000 n 0000401220 00000 n 0000401245 00000 n 0000401461 00000 n 0000401706 00000 n 0000404136 00000 n 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