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This is an open-access article distributed under the terms of the Creative Commons Attribution License, which permits unrestricted use, distribution, and reproduction in any medium, provided the original author and source are credited. 61-year-old female was referred to our center for management of progressing chronic lymphocytic leukemia, diagnosed 4 years ago on lymphocytosis and smudge cells on peripheral blood smear. At initial assessment she had erythematous papulomatous skin rash, hepatosplenomegaly, diffuse lymphadenopathy, pleural effusions. Peripheral blood showed anemia (hemoglobin 110 g/L, mean corpuscular volume 101fL), elevated white blood cell count (199 × 109/mL) with lymphocytosis. Bone marrow examination revealed interstitial and intrasinusoidal marrow infiltration with small to intermediate size mature lymphocytes with minimal cytoplasm, condensed chromatin and indistinct nucleoli. No cells with large nucleoli typical of prolymphocytes were seen. Cells were positive for CD2/3/4/5/7, negative for CD20/23/8, had normal female karyotype. B-cells appeared exceedingly rare. Skin biopsy pleural fluid showed similar findings. Based on morphology and immunohisochemistry provisional diagnosis of mature T-cell lymphoma was made. Because of discordance of laboratory and clinical findings, we requested additional investigations, which showed that cells were positive for TCL-1, CD30. The diagnosis was changed to T-cell prolymphocytic leukemia, small cell variant, without evidence of previously diagnosed chronic lymphocytic leukemia was made. Rouslan Kotchetkov1* and Russell Price2 T-Prolymphocytic Leukemia (T-PLL) Lymphocytosis Chronic Lymphocytic Leukemia (CLL) Smudge Cells 2016-04-07T21:30:20+05:30 2016-04-07T21:30:25+05:30 2016-04-07T21:30:25+05:30 4 Adobe InDesign CS6 (Windows) uuid:fe4ca916-a19d-436d-a200-422a0db30048 xmp.did:FE00469DB0C7E411AEB789ACBE3823B3 xmp.id:CA6CB2A9D9FCE5119ADBC8BC59F48943 proof:pdf converted from application/x-indesign to application/pdf Adobe InDesign CS6 (Windows) / 2016-04-07T21:30:20+05:30 xmp.iid:C96CB2A9D9FCE5119ADBC8BC59F48943 xmp.did:FE00469DB0C7E411AEB789ACBE3823B3 xmp.did:FE00469DB0C7E411AEB789ACBE3823B3 default Rouslan Kotchetkov, Department of Medicine, University of Toronto,Simcoe Muskoka Regional Cancer Program, Georgian Drive, Barrie , Canada, Tel: (705) 728-9090 x 43333; Fax: (705) 739-5630; E-mail: kotchetkovr@rvh.on.ca Citation: Kotchetkov R, Price R (2016) Microcellularvariant of T-Prolymphocytic Leukemia mimickingCLL. 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